Pleural Decortication for Disseminated BCG-osis in a 16 Month-old Infant with Severe Combined Immune Deficiency
Kyung Soo Kim, Ji Yun Lee, Jung Suk Choi, Seung Keun Yun, Seok Whan Moon
Department of Thoracic and Cardiovascular Surgery, Seoul St. Mary’s Hospital, The Catholic University College of Medicine, Seoul, Republic of Korea
Purpose : We report a case of disseminated BCG-osis in infant with severe combined immune deficiency (SCID). The purpose of our presentation is to demonstrate our experience for intractable pleurisy in pleural BCG-osis infant.
Methods : A 16-month-old female (Weight: 6.5 kg, Height: 65.5 cm) presented with fever and pleurisy due to disseminated BCG-osis. Her brother expired in 4 months-old due to SCID, and she received allogeneic bone marrow transplantation at 3 months-old. Neck BCG lymphadenitis was initially presented that anti-tuberculosis treatment was continued. We initially performed VATS for pleurisy, but open pleural decortication was followed 3 months later due to empyema.
Results : The operative time took 140 minutes and the blood loss was 100 ml. We encountered diffuse, whole trapped lung due to fibrotic thickened pleura. The postoperative recovery took 6 months due to pneumonia with sepsis. Finally, lung lesion was gradually improved after prolonged mechanical ventilation that she survived from catastrophic situations.
Conclusion : With a complete pleural decortication, we successfully managed empyema due to pleural BCG-osis in infant with SCID. Proper surgical intervention with meticulous decortication technique should be warranted.

책임저자: Seok Whan Moon
Department of Thoracic and Cardiovascular Surgery, Seoul St. Mary’s Hospital, The Catholic University College of Medicine, Seoul, Republic of Korea
발표자: Kyung Soo Kim, E-mail : cskks@catholic.ac.kr